
Odontogenic Keratocyst (OKC) are defined as epithelial cell lined cysts. Most of these Odontogenic cyst are defined by their history. (OKC) is an entity from the Odontogenicyst, have potential Aggressive behavior and high tendency of recurrence together with defined histopathological features. This article reports a (OKC) in the maxillary sinus. This cyst occurs less than 1% in the maxillary sinus of all cases. The lesion was diagnosed based on histopathological and radiological feature, Treatment was surgically and no recurrence has been observed on follow up.